We report the use of lamotrigine to treat paroxysmal kinesigenic choreoathetosis. Paroxysmal cases of kinesigenic choreoathetosis were first described in 1962 by Lishmanet al 1 and the term “paroxysmal kinesigenic choreoathetosis” was first coined by Kertesz2 in 1967. Recently, a more universal and potentially useful classification of these disorders has been proposed amending the terminology to “paroxysmal kinesigenic dyskinesia”.3 However, we have used the more familiar terminology for our patient as it is more precise. The clinical features of paroxysmal kinesigenic choreoathetosis have been reviewed by Marsden and Luders.4 …