Sporadic corticobasal syndrome due to FTLD-TDP

Acta Neuropathol. 2010 Mar;119(3):365-74. doi: 10.1007/s00401-009-0605-1. Epub 2009 Oct 30.

Abstract

Sporadic corticobasal syndrome (CBS) has been associated with diverse pathological substrates, but frontotemporal lobar degeneration with TDP-43 immunoreactive inclusions (FTLD-TDP) has only been linked to CBS among progranulin mutation carriers. We report the clinical, neuropsychological, imaging, genetic, and neuropathological features of GS, a patient with sporadic corticobasal syndrome. Genetic testing revealed no mutations in the microtubule associated protein tau or progranulin (PGRN) genes, but GS proved homozygous for the T allele of the rs5848 PGRN variant. Autopsy showed ubiquitin and TDP-43 pathology most similar to a pattern previously associated with PGRN mutation carriers. These findings confirm that FTLD-TDP should be included in the pathological differential diagnosis for sporadic CBS.

Publication types

  • Case Reports
  • Research Support, N.I.H., Extramural

MeSH terms

  • Basal Ganglia Diseases / complications*
  • Basal Ganglia Diseases / genetics
  • Brain / pathology
  • Enzyme-Linked Immunosorbent Assay
  • Female
  • Frontotemporal Lobar Degeneration / complications
  • Frontotemporal Lobar Degeneration / genetics
  • Frontotemporal Lobar Degeneration / pathology*
  • Humans
  • Immunohistochemistry
  • Intercellular Signaling Peptides and Proteins / genetics
  • Intercellular Signaling Peptides and Proteins / metabolism
  • Magnetic Resonance Imaging
  • Middle Aged
  • Neurodegenerative Diseases / genetics
  • Neurodegenerative Diseases / pathology
  • Neuropsychological Tests
  • Progranulins
  • TDP-43 Proteinopathies / complications
  • TDP-43 Proteinopathies / genetics
  • TDP-43 Proteinopathies / pathology*
  • tau Proteins / genetics
  • tau Proteins / metabolism

Substances

  • GRN protein, human
  • Intercellular Signaling Peptides and Proteins
  • MAPT protein, human
  • Progranulins
  • tau Proteins